ROGDI

Chr 16AR

rogdi atypical leucine zipper

The ROGDI protein is involved in brain development, neurogenesis, and tooth dentin formation, and is located in the nuclear envelope. Mutations cause Kohlschutter-Tonz syndrome, a rare autosomal recessive disorder characterized by early-onset seizures, intellectual disability, and distinctive dental abnormalities. The gene shows tolerance to loss-of-function variants (very low pLI score), which is consistent with the recessive inheritance pattern observed clinically.

OMIMResearchSummary from RefSeq, OMIM
LOFmechanismARLOEUF 1.421 OMIM phenotype
Clinical SummaryROGDI
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Gene-Disease Validity (ClinGen)
amelocerebrohypohidrotic syndrome · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.42LOEUF
pLI 0.000
Z-score 0.32
OE 0.91 (0.601.42)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-1.32Z-score
OE missense 1.29 (1.151.45)
212 obs / 164.3 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.91 (0.601.42)
00.351.4
Missense OE1.29 (1.151.45)
00.61.4
Synonymous OE1.66
01.21.6
LoF obs/exp: 14 / 15.4Missense obs/exp: 212 / 164.3Syn Z: -4.35

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ROGDI · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
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