RNASEH2B

Chr 13AR

ribonuclease H2 subunit B

Also known as: AGS2, DLEU8

The protein is the non-catalytic B subunit of RNase H2, an endonuclease that degrades RNA from RNA:DNA hybrids and removes ribonucleotides during DNA replication. Mutations cause Aicardi-Goutières syndrome type 2, an early-onset autosomal recessive neuroinflammatory disorder that typically presents in infancy with features resembling congenital infection. The gene is highly intolerant to loss-of-function variants, reflecting its essential role in DNA metabolism.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.251 OMIM phenotype
Clinical SummaryRNASEH2B
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Gene-Disease Validity (ClinGen)
RNASEH2B-related type 1 interferonopathy · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.25LOEUF
pLI 0.000
Z-score 0.76
OE 0.81 (0.541.25)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.24Z-score
OE missense 1.06 (0.931.21)
154 obs / 145.9 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.81 (0.541.25)
00.351.4
Missense OE1.06 (0.931.21)
00.61.4
Synonymous OE1.04
01.21.6
LoF obs/exp: 15 / 18.5Missense obs/exp: 154 / 145.9Syn Z: -0.23

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

RNASEH2B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗