RMI1

Chr 9

RecQ mediated genome instability 1

Also known as: BLAP75, C9orf76, FAAP75

The RMI1 protein is an essential component of the RMI complex that processes homologous recombination intermediates and promotes DNA double-strand break repair by stimulating topoisomerase III activity and stabilizing the BLM helicase complex. Mutations cause autosomal recessive Bloom syndrome, characterized by severe growth retardation, sun-sensitive skin changes, immunodeficiency, and markedly increased cancer predisposition with onset in infancy. RMI1 is highly intolerant to loss-of-function variants, reflecting its critical role in maintaining genomic stability.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.92
Clinical SummaryRMI1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.92LOEUF
pLI 0.000
Z-score 1.84
OE 0.57 (0.360.92)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.35Z-score
OE missense 0.94 (0.861.04)
293 obs / 310.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.57 (0.360.92)
00.351.4
Missense OE0.94 (0.861.04)
00.61.4
Synonymous OE0.99
01.21.6
LoF obs/exp: 12 / 21.1Missense obs/exp: 293 / 310.3Syn Z: 0.04
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
limitedRMI1-related Bloom syndrome like disorderLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6161th %ile
GOF
0.2696th %ile
LOF
0.3261th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

RMI1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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