RIMKLB

Chr 12

ribosomal modification protein rimK like family member B

Also known as: FAM80B, NAAGS, NAAGS-I

The protein catalyzes the synthesis of beta-citryl-L-glutamate and N-acetyl-L-aspartyl-L-glutamate in the cytoplasm. Mutations cause autosomal recessive intellectual disability with seizures and hypotonia, typically presenting in infancy or early childhood. This gene is highly constrained against loss-of-function variants, indicating intolerance to protein disruption.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
1
Pubs (1 yr)
38
P/LP submissions
0%
P/LP missense
0.49
LOEUF
Mechanism
Clinical SummaryRIMKLB
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.59) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
37 unique Pathogenic / Likely Pathogenic· 37 VUS of 85 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.49LOEUF
pLI 0.593
Z-score 2.98
OE 0.19 (0.090.49)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.34Z-score
OE missense 0.57 (0.490.66)
131 obs / 231.1 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.19 (0.090.49)
00.351.4
Missense OE0.57 (0.490.66)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 3 / 15.8Missense obs/exp: 131 / 231.1Syn Z: 0.00

ClinVar Variant Classifications

85 submitted variants in ClinVar

Classification Summary

Pathogenic35
Likely Pathogenic2
VUS37
35
Pathogenic
2
Likely Pathogenic
37
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
35
0
35
Likely Pathogenic
0
0
2
0
2
VUS
0
33
4
0
37
Likely Benign
0
0
0
0
0
Benign
0
0
0
0
0
Total03341074

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

RIMKLB · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC