RFX5

Chr 1AR

regulatory factor X5

Also known as: MHC2D3, MHC2D5

RFX5 encodes the 75-kD subunit of RFX, a nuclear protein complex that activates transcription from MHC class II promoters by binding to X-boxes in the promoter regions. Mutations cause MHC class II deficiency (bare lymphocyte syndrome), an autosomal recessive severe combined immunodeficiency presenting in early infancy with recurrent infections due to absent MHC class II expression on immune cells. The gene shows very low constraint against loss-of-function variants (pLI near zero), consistent with its recessive inheritance pattern.

OMIMResearchSummary from RefSeq, OMIM, UniProt
ARLOEUF 1.102 OMIM phenotypes
Clinical SummaryRFX5
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Gene-Disease Validity (ClinGen)
MHC class II deficiency · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.10LOEUF
pLI 0.000
Z-score 1.14
OE 0.76 (0.531.10)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.48Z-score
OE missense 0.93 (0.841.02)
314 obs / 338.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.76 (0.531.10)
00.351.4
Missense OE0.93 (0.841.02)
00.61.4
Synonymous OE0.75
01.21.6
LoF obs/exp: 20 / 26.3Missense obs/exp: 314 / 338.7Syn Z: 2.23

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

RFX5 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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