RFTN2

Chr 2

raftlin family member 2

Also known as: C2orf11, Raftlin-2

The protein mediates clathrin-dependent internalization of TLR4 upon bacterial stimulation in dendritic cells and may regulate B-cell antigen receptor signaling. Mutations in RFTN2 cause autosomal recessive developmental and epileptic encephalopathy with onset in infancy, characterized by severe intellectual disability, seizures, and brain malformations. This gene shows tolerance to loss-of-function variants in the general population.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.84
Clinical SummaryRFTN2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
36 unique Pathogenic / Likely Pathogenic· 74 VUS of 122 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.84LOEUF
pLI 0.000
Z-score 2.14
OE 0.52 (0.330.84)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.33Z-score
OE missense 0.94 (0.851.05)
256 obs / 271.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.52 (0.330.84)
00.351.4
Missense OE0.94 (0.851.05)
00.61.4
Synonymous OE0.72
01.21.6
LoF obs/exp: 12 / 23.1Missense obs/exp: 256 / 271.3Syn Z: 2.28

ClinVar Variant Classifications

122 submitted variants in ClinVar

Classification Summary

Pathogenic35
Likely Pathogenic1
VUS74
Likely Benign3
35
Pathogenic
1
Likely Pathogenic
74
VUS
3
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
35
0
35
Likely Pathogenic
0
0
1
0
1
VUS
0
70
4
0
74
Likely Benign
0
3
0
0
3
Benign
0
0
0
0
0
Total073400113

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

RFTN2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found