REVSEX

Chr 17AD

reversal of sex (RevSex) determining region

This locus represents the RevSex (Reversal of Sex) sex determining region located approximately 571 kb upstream of the SOX9 (SRY-box transcription factor 9) gene on chromosome 17. Copy number variants (CNVs) that include this region are associated with ovo-testicular disorders of sex development (DSD), where duplications cause 46,XX DSD, while deletions cause 46,XY DSD. This RevSex region represents the minimal critical region found among CNV alterations in 46,XX DSD and 46,XY DSD individuals. It contains multiple sex reversal enhancers, including the most highly conserved subregion, SR4, which was shown to function as a genital tubercle enhancer. It also includes the eSR-B enhancer shown to be active in COS-7 monkey kidney cells, HEK293T human embryonic kidney cells, and TM3 Leydig and TM4 Sertoli testicular cells. The eSR-B enhancer contains a SOX9 motif and can be transactivated by the SOX9 transcription factor alone or by SOX9 and SF1 together, while it is repressed by FOXL2. Furthermore, the eSR-B enhancer displayed synergistic activity with the upstream eSR-A and downstream eALDI enhancers in the presence of SOX9 and SF1, suggesting that these enhancers may function cooperatively to regulate transcription of the SOX9 gene. [provided by RefSeq, Aug 2023]

Primary Disease Associations & Inheritance

46XY sex reversal 10MIM #616425
AD
46XX sex reversal 2MIM #278850
AD
46XX sex reversal 2MIM #278850
AD
46XY sex reversal 10MIM #616425
AD
Acampomelic campomelic dysplasiaMIM #114290
AD
Campomelic dysplasiaMIM #114290
AD
Campomelic dysplasia with autosomal sex reversalMIM #114290
AD
0
Active trials
6
Pathogenic / LP
6
ClinVar variants
1
Pubs (1 yr)
Missense Z
LOEUF
Clinical SummaryREVSEX
📋
ClinVar Variants
6 Pathogenic / Likely Pathogenic of 6 total submissions
Some data sources returned errors (2)

ensembl: Error: Ensembl fetch failed: 400 for https://rest.ensembl.org/lookup/symbol/homo_sapiens/REVSEX?content-type=application/json&expand=1

gnomad: Error: Gene not found

Population Genetics & Constraint

Constraint data not available from gnomAD.

ClinVar Variant Classifications

6 submitted variants in ClinVar

Classification Summary

Pathogenic6
6
Pathogenic

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
6
Likely Pathogenic
0
VUS
0
Likely Benign
0
Benign
0
Total6

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

REVSEX · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
Landmark / reviewRecent case evidence
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC