RASD1

Chr 17

ras related dexamethasone induced 1

Also known as: AGS1, DEXRAS1, MGC:26290

The RASD1 protein is a small GTPase that activates G-protein signaling and acts as a nucleotide exchange factor for Gi-Go proteins. Mutations in RASD1 cause neurodevelopmental disorders with intellectual disability, typically presenting in early childhood. The gene follows an autosomal dominant inheritance pattern.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.18
Clinical SummaryRASD1
Population Constraint (gnomAD)
Low constraint (pLI 0.04) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
69 unique Pathogenic / Likely Pathogenic of 69 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.18LOEUF
pLI 0.039
Z-score 1.28
OE 0.46 (0.211.18)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.37Z-score
OE missense 0.92 (0.811.05)
160 obs / 173.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.46 (0.211.18)
00.351.4
Missense OE0.92 (0.811.05)
00.61.4
Synonymous OE0.96
01.21.6
LoF obs/exp: 3 / 6.5Missense obs/exp: 160 / 173.9Syn Z: 0.28
DN
0.80top 25%
GOF
0.79top 25%
LOF
0.3162th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

69 submitted variants in ClinVar

Classification Summary

Pathogenic69
69
Pathogenic

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
69
Likely Pathogenic
0
VUS
0
Likely Benign
0
Benign
0
Total69

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

RASD1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →