RARS2

Chr 6AR

arginyl-tRNA synthetase 2, mitochondrial

Also known as: ArgRS, DALRD2, PCH6, PRO1992, RARSL

This nuclear gene encodes a protein that localizes to the mitochondria, where it catalyzes the transfer of L-arginine to its cognate tRNA, an important step in translation of mitochondrially-encoded proteins. Defects in this gene are a cause of pontocerebellar hypoplasia type 6 (PCH6). Alternative splicing results in multiple transcript variants. [provided by RefSeq, Jan 2016]

OMIMResearchGenerating clinical summary…
LOFmechanismARLOEUF 0.921 OMIM phenotype
Clinical SummaryRARS2
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
0.92LOEUF
pLI 0.000
Z-score 1.95
OE 0.67 (0.490.92)
Tolerant

Typical tolerance to LoF variation

Missense Constraint?
-0.06Z-score
OE missense 1.01 (0.921.11)
308 obs / 304.8 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios?
LoF OE?0.67 (0.490.92)
00.351.4
Missense OE?1.01 (0.921.11)
00.61.4
Synonymous OE?1.09
01.21.6
LoF obs/exp: 27 / 40.3Missense obs/exp: 308 / 304.8Syn Z: -0.73
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveRARS2-related pontocerebellar hypoplasiaLOFAR

This gene — mechanism propensity

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6842th %ile
GOF
0.6248th %ile
LOF
0.2971th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

RARS2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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