PTAR1

Chr 9

protein prenyltransferase alpha subunit repeat containing 1

The protein serves as the substrate-recognition subunit of geranylgeranyl transferase type 3, which modifies specific proteins like FBXL2 and YKT6 to target them to cellular membranes and enable proper Golgi function. Mutations cause autosomal recessive intellectual disability with progressive spasticity and optic atrophy, typically presenting in early childhood. The gene is highly constrained against loss-of-function variants, indicating that complete loss of protein function is likely incompatible with normal development.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.39
Clinical SummaryPTAR1
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.86) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
41 unique Pathogenic / Likely Pathogenic· 55 VUS of 107 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.39LOEUF
pLI 0.864
Z-score 3.49
OE 0.15 (0.070.39)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.44Z-score
OE missense 0.72 (0.630.82)
148 obs / 206.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.15 (0.070.39)
00.351.4
Missense OE0.72 (0.630.82)
00.61.4
Synonymous OE0.93
01.21.6
LoF obs/exp: 3 / 19.7Missense obs/exp: 148 / 206.4Syn Z: 0.45

ClinVar Variant Classifications

107 submitted variants in ClinVar

Classification Summary

Pathogenic33
Likely Pathogenic8
VUS55
Likely Benign1
33
Pathogenic
8
Likely Pathogenic
55
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
33
0
33
Likely Pathogenic
0
0
8
0
8
VUS
1
52
2
0
55
Likely Benign
0
1
0
0
1
Benign
0
0
0
0
0
Total15343097

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PTAR1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found