PRPF38A

Chr 1

pre-mRNA processing factor 38A

Also known as: PRP38A, Prp38

The PRPF38A protein is a component of the spliceosome that binds RNA and is involved in pre-mRNA splicing within the nucleoplasm. Mutations cause autosomal recessive retinitis pigmentosa, a progressive retinal degeneration leading to vision loss. The gene shows significant constraint against loss-of-function variants (LOEUF 0.408), indicating that complete loss of function is likely poorly tolerated.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.41
Clinical SummaryPRPF38A
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.77) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
7 unique Pathogenic / Likely Pathogenic· 38 VUS of 59 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.41LOEUF
pLI 0.772
Z-score 3.61
OE 0.18 (0.090.41)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.11Z-score
OE missense 0.58 (0.490.68)
114 obs / 197.4 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.18 (0.090.41)
00.351.4
Missense OE0.58 (0.490.68)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 4 / 22.5Missense obs/exp: 114 / 197.4Syn Z: 0.19
DN
0.3991th %ile
GOF
0.4282th %ile
LOF
0.70top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.41

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

59 submitted variants in ClinVar

Classification Summary

Pathogenic5
Likely Pathogenic2
VUS38
Likely Benign1
5
Pathogenic
2
Likely Pathogenic
38
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
5
0
5
Likely Pathogenic
0
0
2
0
2
VUS
0
36
2
0
38
Likely Benign
0
0
0
1
1
Benign
0
0
0
0
0
Total0369146

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PRPF38A · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found