PRORP

Chr 14AR

protein only RNase P catalytic subunit

Also known as: COXPD54, KIAA0391, MRPP3

This protein serves as the catalytic ribonuclease component of mitochondrial ribonuclease P, which cleaves the 5' ends of mitochondrial tRNA molecules as part of tRNA processing. Biallelic mutations cause combined oxidative phosphorylation deficiency 54, an autosomal recessive mitochondrial disorder affecting cellular energy production. The gene shows relaxed constraint against loss-of-function variants (LOEUF 1.222), and a comprehensive clinical review is available in GeneReviews.

OMIMResearchSummary from RefSeq, OMIM, UniProt
DNmechanismARLOEUF 1.221 OMIM phenotype
Clinical SummaryPRORP
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.22LOEUF
pLI 0.000
Z-score 0.68
OE 0.86 (0.611.22)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.78Z-score
OE missense 0.88 (0.790.97)
270 obs / 308.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.86 (0.611.22)
00.351.4
Missense OE0.88 (0.790.97)
00.61.4
Synonymous OE0.90
01.21.6
LoF obs/exp: 22 / 25.7Missense obs/exp: 270 / 308.4Syn Z: 0.79
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
limitedPRORP-related mitochondrial disorderOTHERAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6744th %ile
GOF
0.5170th %ile
LOF
0.2581th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PRORP · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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