PRODH

Chr 22

proline dehydrogenase 1

Also known as: HSPOX2, PIG6, POX, PRODH1, TP53I6

This gene encodes a mitochondrial protein that catalyzes the first step in proline degradation. Mutations in this gene are associated with hyperprolinemia type 1 and susceptibility to schizophrenia 4 (SCZD4). This gene is located on chromosome 22q11.21, a region which has also been associated with the contiguous gene deletion syndromes, DiGeorge and CATCH22. Alternatively spliced transcript variants encoding different isoforms have been found for this gene. [provided by RefSeq, Aug 2010]

GeneReviewsResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

UniProtHyperprolinemia 1
UniProtSchizophrenia 4

Clinical highlights

Gene-disease validity (ClinGen)
hyperprolinemia type 1 · ARDefinitivesufficient evidence for diagnostic panels
0
Active trials
36
Pubs (1 yr)
P/LP submissions
P/LP missense
1.10
LOEUF
DN
Mechanism· predicted
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GeneReview available — PRODH
Authoritative clinical overview · Recommended first read
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Some data sources returned errors (1)

omim: Error: OMIM fetch failed: 429

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
1.10LOEUF
pLI 0.000
Z-score 1.15
OE 0.76 (0.541.10)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint?
0.06Z-score
OE missense 0.99 (0.901.09)
307 obs / 310.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios?
LoF OE?0.76 (0.541.10)
00.351.4
Missense OE?0.99 (0.901.09)
00.61.4
Synonymous OE?1.09
01.21.6
LoF obs/exp: 21 / 27.5Missense obs/exp: 307 / 310.2Syn Z: -0.79

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PRODH · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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