PRM1

Chr 16

protamine 1

Also known as: CT94.1, P1

Protamine 1 substitutes for histones to compact sperm DNA into a highly condensed, stable complex during spermatogenesis. Mutations in PRM1 cause male infertility due to defective sperm chromatin condensation, inherited in an autosomal recessive pattern. The gene shows low constraint to loss-of-function variation, consistent with its tissue-specific expression limited to male reproductive cells.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.87
Clinical SummaryPRM1
Population Constraint (gnomAD)
Low constraint (pLI 0.03) — loss-of-function variants are relatively tolerated in the population.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.87LOEUF
pLI 0.027
Z-score 0.07
OE 0.95 (0.351.87)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.54Z-score
OE missense 1.25 (0.981.60)
45 obs / 36.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.95 (0.351.87)
00.351.4
Missense OE1.25 (0.981.60)
00.61.4
Synonymous OE1.63
01.21.6
LoF obs/exp: 2 / 2.1Missense obs/exp: 45 / 36.0Syn Z: -1.60
DN
0.75top 25%
GOF
0.1699th %ile
LOF
0.1796th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PRM1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
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