POM121

Chr 7

POM121 transmembrane nucleoporin

Also known as: P145, POM121A

The protein is a transmembrane component of the nuclear pore complex that anchors the complex to the nuclear envelope and mediates nuclear transport. Mutations cause autosomal recessive developmental delay with dysmorphic facies and dental anomalies, typically presenting in early childhood. The gene shows moderate constraint against loss-of-function variants, suggesting some tolerance to haploinsufficiency.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.53
Clinical SummaryPOM121
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.28) despite low pLI — interpret in context.
📋
ClinVar Variants
27 unique Pathogenic / Likely Pathogenic· 83 VUS of 147 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.53LOEUF
pLI 0.058
Z-score 3.33
OE 0.28 (0.160.53)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
-0.97Z-score
OE missense 1.13 (1.051.21)
536 obs / 476.1 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.28 (0.160.53)
00.351.4
Missense OE1.13 (1.051.21)
00.61.4
Synonymous OE1.24
01.21.6
LoF obs/exp: 7 / 25.0Missense obs/exp: 536 / 476.1Syn Z: -2.72

ClinVar Variant Classifications

147 submitted variants in ClinVar

Classification Summary

Pathogenic24
Likely Pathogenic3
VUS83
Likely Benign11
Benign7
24
Pathogenic
3
Likely Pathogenic
83
VUS
11
Likely Benign
7
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
24
0
24
Likely Pathogenic
0
0
3
0
3
VUS
0
80
3
0
83
Likely Benign
1
9
0
1
11
Benign
0
4
2
1
7
Total193322128

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

POM121 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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