POLR2K

Chr 8

RNA polymerase II, I and III subunit K

Also known as: ABC10-alpha, RPABC4, RPB10alpha, RPB12, RPB7.0, hRPB7.0, hsRPB10a

The POLR2K protein is a small subunit shared by all three RNA polymerases (I, II, and III) that catalyzes transcription of DNA into various RNA species including mRNA, ribosomal RNA, and transfer RNA. Mutations cause autosomal recessive developmental and epileptic encephalopathy with onset in early infancy, characterized by severe intellectual disability, refractory seizures, and progressive microcephaly. The gene shows tolerance to loss-of-function variants in the general population, suggesting that biallelic mutations are required for disease manifestation.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
38
P/LP submissions
P/LP missense
1.88
LOEUF
DN
Mechanism· predicted
Clinical SummaryPOLR2K
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
37 unique Pathogenic / Likely Pathogenic· 11 VUS of 54 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.88LOEUF
pLI 0.001
Z-score -0.23
OE 1.13 (0.531.88)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.60Z-score
OE missense 0.70 (0.501.00)
22 obs / 31.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.13 (0.531.88)
00.351.4
Missense OE0.70 (0.501.00)
00.61.4
Synonymous OE1.09
01.21.6
LoF obs/exp: 4 / 3.5Missense obs/exp: 22 / 31.4Syn Z: -0.21
DN
0.6938th %ile
GOF
0.6053th %ile
LOF
0.51top 25%

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

54 submitted variants in ClinVar

Classification Summary

Pathogenic36
Likely Pathogenic1
VUS11
36
Pathogenic
1
Likely Pathogenic
11
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
36
Likely Pathogenic
1
VUS
11
Likely Benign
0
Benign
0
Total48

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

POLR2K · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found