POGLUT1

Chr 3ADAR

protein O-glucosyltransferase 1

Also known as: C3orf9, CLP46, KDELCL1, KTELC1, LGMD2Z, LGMDR21, MDS010, MDSRP

This gene encodes a protein with both O-glucosyltransferase and O-xylosyltransferase activity which localizes to the lumen of the endoplasmic reticulum. This protein has a carboxy-terminal KTEL motif which is predicted to function as an endoplasmic reticulum retention signal. This gene is an essential regulator of Notch signalling and likely plays a role in cell fate and tissue formation during development. It may also play a role in the pathogenesis of leukemia. Mutations in this gene have been associated with the autosomal dominant genodermatosis Dowling-Degos disease 4. Alternative splicing results in multiple transcript variants. [provided by RefSeq, Apr 2014]

GeneReviewsOMIMResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

Dowling-Degos disease 4MIM #615696
AD
Muscular dystrophy, limb-girdle, autosomal recessive 21MIM #617232
AR

Clinical highlights

Gene-disease validity (ClinGen)
autosomal recessive limb-girdle muscular dystrophy · ARDefinitivesufficient evidence for diagnostic panels
0
Active trials
7
Pubs (1 yr)
P/LP submissions
P/LP missense
0.89
LOEUF
DN
Mechanism· predicted
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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
0.89LOEUF
pLI 0.000
Z-score 2.00
OE 0.60 (0.410.89)
Tolerant

Typical tolerance to LoF variation

Missense Constraint?
1.15Z-score
OE missense 0.78 (0.680.89)
164 obs / 211.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios?
LoF OE?0.60 (0.410.89)
00.351.4
Missense OE?0.78 (0.680.89)
00.61.4
Synonymous OE?1.12
01.21.6
LoF obs/exp: 17 / 28.6Missense obs/exp: 164 / 211.0Syn Z: -0.83

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

POGLUT1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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