PLEKHO1

Chr 1

pleckstrin homology domain containing O1

Also known as: CKIP-1, CKIP1, JBP, OC120

Predicted to be involved in regulation of myoblast fusion. Predicted to act upstream of or within several processes, including lamellipodium morphogenesis; myoblast fusion; and myoblast migration. Predicted to be located in cytoplasm; nucleus; and plasma membrane. Predicted to be active in muscle cell projection membrane and ruffle membrane. [provided by Alliance of Genome Resources, Jul 2025]

ResearchGenerating clinical summary…
LOEUF 0.48
Clinical SummaryPLEKHO1
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.21) despite low pLI — interpret in context.
📋
ClinVar Variants
65 VUS of 77 total submissions
Some data sources returned errors (1)

omim: Error: OMIM fetch failed: 429

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint?
0.48LOEUF
pLI 0.483
Z-score 3.19
OE 0.21 (0.100.48)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint?
0.07Z-score
OE missense 0.99 (0.891.10)
244 obs / 247.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios?
LoF OE?0.21 (0.100.48)
00.351.4
Missense OE?0.99 (0.891.10)
00.61.4
Synonymous OE?1.04
01.21.6
LoF obs/exp: 4 / 19.0Missense obs/exp: 244 / 247.1Syn Z: -0.29

ClinVar Variant Classifications

77 submitted variants in ClinVar

Classification Summary

VUS65
Likely Benign3
Benign2
65
VUS
3
Likely Benign
2
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
0
0
0
Likely Pathogenic
0
0
0
0
0
VUS
0
65
0
0
65
Likely Benign
0
1
0
2
3
Benign
0
0
1
1
2
Total0661370

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

13 pathogenic / likely-pathogenic (of 19) ClinVar copy-number / structural variants overlap PLEKHO1 — these span large chromosomal regions, not the gene specifically, and are excluded from the counts above. Explore in CNV tools →

Protein Context — Lollipop Plot

PLEKHO1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →