PKD1L3

Chr 16

polycystin 1 like 3, transient receptor potential channel interacting

This gene encodes a member of the polycystin protein family. The encoded protein contains 11 transmembrane domains, a latrophilin/CL-1-like GPCR proteolytic site (GPS) domain, and a polycystin-1, lipoxygenase, alpha-toxin (PLAT) domain. This protein may function as a component of cation channel pores.[provided by RefSeq, Apr 2009]

0
Active trials
28
Pathogenic / LP
334
ClinVar variants
2
Pubs (1 yr)
Missense Z
LOEUF
Clinical SummaryPKD1L3
📋
ClinVar Variants
28 Pathogenic / Likely Pathogenic· 273 VUS of 334 total submissions

Population Genetics & Constraint

Constraint data not available from gnomAD.

DN
0.6936th %ile
GOF
0.6638th %ile
LOF
0.2969th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

334 submitted variants in ClinVar

Classification Summary

Pathogenic25
Likely Pathogenic3
VUS273
Likely Benign25
Benign6
Conflicting2
25
Pathogenic
3
Likely Pathogenic
273
VUS
25
Likely Benign
6
Benign
2
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
25
0
25
Likely Pathogenic
0
0
3
0
3
VUS
0
260
13
0
273
Likely Benign
1
23
1
0
25
Benign
2
2
1
1
6
Conflicting
2
Total3285431334

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PKD1L3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Landmark / reviewRecent case evidence