PJVK

Chr 2AR

pejvakin

Also known as: DFNB59

The protein encoded by PJVK is a peroxisome-associated protein that protects auditory hair cells against noise-induced damage by regulating peroxisome proliferation and promoting autophagy of oxidatively damaged peroxisomes. Mutations cause autosomal recessive non-syndromic sensorineural hearing loss (DFNB59). The gene shows low constraint to loss-of-function variants, consistent with its autosomal recessive inheritance pattern.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.151 OMIM phenotype
Clinical SummaryPJVK
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Gene-Disease Validity (ClinGen)
nonsyndromic genetic hearing loss · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
54 unique Pathogenic / Likely Pathogenic· 65 VUS of 234 total submissions
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GeneReview available — PJVK
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.15LOEUF
pLI 0.000
Z-score 1.07
OE 0.73 (0.481.15)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.13Z-score
OE missense 0.97 (0.861.10)
181 obs / 186.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.73 (0.481.15)
00.351.4
Missense OE0.97 (0.861.10)
00.61.4
Synonymous OE0.88
01.21.6
LoF obs/exp: 14 / 19.1Missense obs/exp: 181 / 186.1Syn Z: 0.77

ClinVar Variant Classifications

234 submitted variants in ClinVar

Classification Summary

Pathogenic38
Likely Pathogenic16
VUS65
Likely Benign103
Benign2
Conflicting9
38
Pathogenic
16
Likely Pathogenic
65
VUS
103
Likely Benign
2
Benign
9
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
22
2
14
0
38
Likely Pathogenic
11
1
3
1
16
VUS
1
58
6
0
65
Likely Benign
0
3
34
66
103
Benign
0
0
2
0
2
Conflicting
9
Total34645967233

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PJVK · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗