PIGA

Chr XXLR

phosphatidylinositol glycan anchor biosynthesis class A

Also known as: GPI3, MCAHS2, NEDEPH, PIG-A, PNH1

The protein is essential for the first step of GPI anchor biosynthesis, catalyzing the synthesis of N-acetylglucosaminyl phosphatidylinositol (GlcNAc-PI), which is required for anchoring proteins to cell surfaces. Germline mutations cause X-linked recessive multiple congenital anomalies-hypotonia-seizures syndrome and neurodevelopmental disorder with epilepsy and hemochromatosis, while somatic mutations lead to the acquired hematologic condition paroxysmal nocturnal hemoglobinuria. Disease predominantly results from loss-of-function mutations disrupting GPI anchor synthesis.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
LOFmechanismXLRLOEUF 0.303 OMIM phenotypes
Clinical SummaryPIGA
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Gene-Disease Validity (ClinGen)
complex neurodevelopmental disorder · XLDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.96). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
4 active or recruiting trials — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.30LOEUF
pLI 0.961
Z-score 2.95
OE 0.00 (0.000.30)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.17Z-score
OE missense 0.56 (0.470.65)
105 obs / 188.9 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.00 (0.000.30)
00.351.4
Missense OE0.56 (0.470.65)
00.61.4
Synonymous OE0.75
01.21.6
LoF obs/exp: 0 / 10.1Missense obs/exp: 105 / 188.9Syn Z: 1.61
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitivePIGA-related multiple congenital anomalies-hypotonia-seizures syndromeLOFXLR
DN
0.4587th %ile
GOF
0.4480th %ile
LOF
0.64top 25%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.30

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PIGA · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Paroxysmal nocturnal haemoglobinuria.
Hill A et al.·Nat Rev Dis Primers
2017Review
X-Linked Epilepsies: A Narrative Review.
Bernardo P et al.·Int J Mol Sci
2024Review
Paroxysmal Nocturnal Hemoglobinuria: Biology and Treatment.
Bravo-Perez C et al.·Medicina (Kaunas)
2023Review
Top 5 results · since 2015Search PubMed ↗