PHB2

Chr 12

prohibitin 2

Also known as: BAP, BCAP37, Bap37, PNAS-141, REA, hBAP, p22

PHB2 encodes prohibitin-2, a multifunctional protein that serves as a mitochondrial chaperone, functions in cell signaling at the plasma membrane, and acts as a transcriptional co-regulator in the nucleus. Mutations cause spastic paraplegia 35, an autosomal recessive disorder characterized by progressive spasticity primarily affecting the lower limbs. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.655), consistent with its essential cellular functions across multiple compartments.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
58
Pubs (1 yr)
46
P/LP submissions
0%
P/LP missense
0.66
LOEUF
DN
Mechanism· predicted
Clinical SummaryPHB2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
45 unique Pathogenic / Likely Pathogenic· 37 VUS of 97 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.66LOEUF
pLI 0.004
Z-score 2.77
OE 0.36 (0.210.66)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.99Z-score
OE missense 0.58 (0.490.68)
102 obs / 176.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.36 (0.210.66)
00.351.4
Missense OE0.58 (0.490.68)
00.61.4
Synonymous OE0.85
01.21.6
LoF obs/exp: 8 / 22.0Missense obs/exp: 102 / 176.2Syn Z: 0.96
DN
0.83top 10%
GOF
0.4972th %ile
LOF
0.3163th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

97 submitted variants in ClinVar

Classification Summary

Pathogenic43
Likely Pathogenic2
VUS37
Benign3
43
Pathogenic
2
Likely Pathogenic
37
VUS
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
43
0
43
Likely Pathogenic
0
0
2
0
2
VUS
0
25
12
0
37
Likely Benign
0
0
0
0
0
Benign
1
0
0
2
3
Total12557285

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PHB2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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