PGBD3

Chr 10ADARSomatic

piggyBac transposable element derived 3

The protein is a transposon-derived transcriptional regulator that binds to specific transposable DNA elements and can form fusion transcripts with the adjacent DNA repair gene ERCC6. Mutations cause cerebrooculofacioskeletal syndrome, Cockayne syndrome type B, De Sanctis-Cacchione syndrome, and UV-sensitive syndrome, which are multisystem disorders affecting neurological development, growth, and DNA repair with early childhood onset. The gene shows both autosomal recessive and autosomal dominant inheritance patterns depending on the specific condition.

Summary from RefSeq, OMIM, UniProt
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Primary Disease Associations & Inheritance

Premature ovarian failure 11MIM #616946
AD
?De Sanctis-Cacchione syndromeMIM #278800
AR
{Lung cancer, susceptibility to}MIM #211980
ADSomatic
{Macular degeneration, age-related, susceptibility to, 5}MIM #613761
Cerebrooculofacioskeletal syndrome 1MIM #214150
AR
Cockayne syndrome, type BMIM #133540
AR
Premature ovarian failure 11MIM #616946
AD
UV-sensitive syndrome 1MIM #600630
AR
0
Active trials
0
Pubs (1 yr)
96
P/LP submissions
1%
P/LP missense
1.75
LOEUF
Mechanism
Clinical SummaryPGBD3
Population Constraint (gnomAD)
Low constraint (pLI 0.04) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
86 unique Pathogenic / Likely Pathogenic· 151 VUS of 315 total submissions
Some data sources returned errors (1)

ensembl: Error: Ensembl fetch failed: 400 for https://rest.ensembl.org/lookup/symbol/homo_sapiens/PGBD3?content-type=application/json&expand=1

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.75LOEUF
pLI 0.041
Z-score 0.49
OE 0.69 (0.271.75)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.49Z-score
OE missense 0.93 (0.841.02)
313 obs / 338.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.69 (0.271.75)
00.351.4
Missense OE0.93 (0.841.02)
00.61.4
Synonymous OE1.12
01.21.6
LoF obs/exp: 2 / 2.9Missense obs/exp: 313 / 338.1Syn Z: -1.05

ClinVar Variant Classifications

315 submitted variants in ClinVar

Classification Summary

Pathogenic49
Likely Pathogenic37
VUS151
Likely Benign58
Benign10
Conflicting9
49
Pathogenic
37
Likely Pathogenic
151
VUS
58
Likely Benign
10
Benign
9
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
3
1
45
0
49
Likely Pathogenic
10
0
27
0
37
VUS
1
109
41
0
151
Likely Benign
0
6
5
47
58
Benign
0
3
6
1
10
Conflicting
9
Total1411912448314

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PGBD3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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