PEX14

Chr 1AR

peroxisomal biogenesis factor 14

Also known as: NAPP2, PBD13A, Pex14p, dJ734G22.2

The protein is an essential component of the peroxisomal import machinery that integrates into peroxisome membranes and interacts with cytosolic receptors for proteins containing PTS1 peroxisomal targeting signals. Mutations cause peroxisome biogenesis disorder 13A (Zellweger syndrome), inherited in an autosomal recessive pattern. The pathogenic mechanism involves disruption of peroxisomal protein import, leading to defective peroxisome biogenesis.

OMIMResearchSummary from RefSeq, OMIM, UniProt
MultiplemechanismARLOEUF 0.521 OMIM phenotype
Clinical SummaryPEX14
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Gene-Disease Validity (ClinGen)
peroxisome biogenesis disorder · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.25) despite low pLI — interpret in context.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.52LOEUF
pLI 0.226
Z-score 3.15
OE 0.25 (0.130.52)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.27Z-score
OE missense 0.76 (0.670.86)
168 obs / 221.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.25 (0.130.52)
00.351.4
Missense OE0.76 (0.670.86)
00.61.4
Synonymous OE1.12
01.21.6
LoF obs/exp: 5 / 20.3Missense obs/exp: 168 / 221.3Syn Z: -0.91

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PEX14 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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