PEX11B

Chr 1AR

peroxisomal biogenesis factor 11 beta

Also known as: PEX11-BETA, PEX11beta, PEX14B

The protein facilitates peroxisomal proliferation by promoting membrane protrusion and elongation on the peroxisomal surface and recruiting dynamin-related GTPase to regulate peroxisome division. Mutations cause peroxisome biogenesis disorder 14B, inherited in an autosomal recessive pattern. The gene shows relatively low constraint to loss-of-function variants (pLI 0.0001, LOEUF 1.08), suggesting the disorder requires biallelic loss of function.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.081 OMIM phenotype
Clinical SummaryPEX11B
🧬
Gene-Disease Validity (ClinGen)
peroxisome biogenesis disorder · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
150 unique Pathogenic / Likely Pathogenic· 202 VUS of 477 total submissions
📖
GeneReview available — PEX11B
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.08LOEUF
pLI 0.000
Z-score 1.36
OE 0.60 (0.351.08)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.31Z-score
OE missense 1.07 (0.941.22)
156 obs / 145.6 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.60 (0.351.08)
00.351.4
Missense OE1.07 (0.941.22)
00.61.4
Synonymous OE0.85
01.21.6
LoF obs/exp: 8 / 13.4Missense obs/exp: 156 / 145.6Syn Z: 0.90
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitivePEX11B-related peroxisome biogenesis disorder 14BLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.80top 25%
GOF
0.6736th %ile
LOF
0.2679th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

477 submitted variants in ClinVar

Classification Summary

Pathogenic118
Likely Pathogenic32
VUS202
Likely Benign101
Benign8
Conflicting12
118
Pathogenic
32
Likely Pathogenic
202
VUS
101
Likely Benign
8
Benign
12
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
3
0
115
0
118
Likely Pathogenic
10
1
21
0
32
VUS
1
125
72
4
202
Likely Benign
0
1
39
61
101
Benign
0
0
7
1
8
Conflicting
12
Total1412725466473

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PEX11B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →