PDSS1

Chr 10AR

decaprenyl diphosphate synthase subunit 1

Also known as: COQ1, COQ10D2, COQ1A, DPS, SPS, TPRT, TPT, TPT 1

The encoded enzyme catalyzes the condensation of farnesyl diphosphate and isopentenyl diphosphate to produce prenyl diphosphates that serve as precursors for the side chains of ubiquinone-9 and ubiquinone-10 (coenzyme Q), essential components of the mitochondrial respiratory chain. Mutations cause primary coenzyme Q10 deficiency type 2, a multisystem disorder that can present with encephalomyopathy, nephropathy, and cerebellar ataxia. This condition follows autosomal recessive inheritance.

OMIMResearchSummary from RefSeq, OMIM, UniProt
DNmechanismARLOEUF 0.931 OMIM phenotype
Clinical SummaryPDSS1
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.93LOEUF
pLI 0.000
Z-score 1.85
OE 0.61 (0.410.93)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.32Z-score
OE missense 0.75 (0.660.85)
161 obs / 215.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.61 (0.410.93)
00.351.4
Missense OE0.75 (0.660.85)
00.61.4
Synonymous OE0.89
01.21.6
LoF obs/exp: 16 / 26.2Missense obs/exp: 161 / 215.5Syn Z: 0.77
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
strongPDSS1-related coenzyme Q10 deficiency, primaryOTHERAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.74top 25%
GOF
0.5758th %ile
LOF
0.3260th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PDSS1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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