PDP1

Chr 8AR

pyruvate dehydrogenase phosphatase catalytic subunit 1

Also known as: PDH, PDP, PDPC, PDPC 1, PPM2A, PPM2C

The pyruvate dehydrogenase phosphatase catalytic subunit dephosphorylates and activates the E1 component of the pyruvate dehydrogenase complex, which is essential for converting pyruvate to acetyl-CoA in mitochondrial energy metabolism. Mutations cause pyruvate dehydrogenase phosphatase deficiency with autosomal recessive inheritance. This disorder affects cellular energy production and typically involves neurological manifestations due to impaired mitochondrial function.

Summary from RefSeq, OMIM, UniProt
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Primary Disease Associations & Inheritance

Pyruvate dehydrogenase phosphatase deficiencyMIM #608782
AR
0
Active trials
10
Pubs (1 yr)
46
P/LP submissions
0%
P/LP missense
LOEUF
Mechanism
Clinical SummaryPDP1
📋
ClinVar Variants
45 unique Pathogenic / Likely Pathogenic· 107 VUS of 247 total submissions
📖
GeneReview available — PDP1
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Some data sources returned errors (1)

gnomad: Error: Service overloaded

Population Genetics & Constraint

Constraint data not available from gnomAD.

ClinVar Variant Classifications

247 submitted variants in ClinVar

Classification Summary

Pathogenic40
Likely Pathogenic5
VUS107
Likely Benign83
Benign4
Conflicting4
40
Pathogenic
5
Likely Pathogenic
107
VUS
83
Likely Benign
4
Benign
4
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
40
0
40
Likely Pathogenic
3
0
2
0
5
VUS
2
95
10
0
107
Likely Benign
0
0
7
76
83
Benign
0
0
4
0
4
Conflicting
4
Total5956376243

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

PDP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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