PDHB

Chr 3AR

pyruvate dehydrogenase E1 subunit beta

Also known as: E1beta, PDHBD, PDHE1-B, PDHE1B, PHE1B

The pyruvate dehydrogenase (PDH) complex is a nuclear-encoded mitochondrial multienzyme complex that catalyzes the overall conversion of pyruvate to acetyl-CoA and carbon dioxide, and provides the primary link between glycolysis and the tricarboxylic acid (TCA) cycle. The PDH complex is composed of multiple copies of three enzymatic components: pyruvate dehydrogenase (E1), dihydrolipoamide acetyltransferase (E2) and lipoamide dehydrogenase (E3). The E1 enzyme is a heterotetramer of two alpha and two beta subunits. This gene encodes the E1 beta subunit. Mutations in this gene are associated with pyruvate dehydrogenase E1-beta deficiency. Alternatively spliced transcript variants have been found for this gene. [provided by RefSeq, Mar 2012]

GeneReviewsOMIMResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

Pyruvate dehydrogenase E1-beta deficiencyMIM #614111
AR

Clinical highlights

Gene-disease validity (ClinGen)
Leigh syndrome · ARModerateconsider for supplementary testing
Interpreting a novel variant
This gene is strongly intolerant of loss-of-function variation in the population, so LoF variants warrant close attention. No curated mechanism annotation is available — see the mechanism card for the computational prediction and its caveats.Based on population constraint only.
0
Active trials
48
Pubs (1 yr)
P/LP submissions
P/LP missense
0.55
LOEUF
DN
Mechanism· predicted
📖
GeneReview available — PDHB
Authoritative clinical overview · Recommended first read
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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint?
0.55LOEUF
pLI 0.152
Z-score 2.98
OE 0.26 (0.140.55)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint?
1.57Z-score
OE missense 0.69 (0.600.79)
139 obs / 201.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios?
LoF OE?0.26 (0.140.55)
00.351.4
Missense OE?0.69 (0.600.79)
00.61.4
Synonymous OE?1.13
01.21.6
LoF obs/exp: 5 / 19.0Missense obs/exp: 139 / 201.6Syn Z: -0.85

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

PDHB · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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