P3H3

Chr 12

prolyl 3-hydroxylase 3

Also known as: GRCB, HSU47926, LEPREL2

The protein encoded by this gene belongs to the leprecan family of proteoglycans, which function as collagen prolyl hydroxylases that are required for proper collagen biosynthesis, folding and assembly. This protein, like other family members, is thought to reside in the endoplasmic reticulum. Epigenetic inactivation of this gene is associated with breast and other cancers, suggesting that it may function as a tumor suppressor. [provided by RefSeq, Aug 2013]

0
Active trials
1
Pubs (1 yr)
45
P/LP submissions
0%
P/LP missense
1.01
LOEUF
Mechanism
Clinical SummaryP3H3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
45 unique Pathogenic / Likely Pathogenic· 57 VUS of 127 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.01LOEUF
pLI 0.000
Z-score 1.51
OE 0.71 (0.501.01)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.04Z-score
OE missense 1.01 (0.921.10)
363 obs / 361.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.71 (0.501.01)
00.351.4
Missense OE1.01 (0.921.10)
00.61.4
Synonymous OE0.98
01.21.6
LoF obs/exp: 22 / 31.1Missense obs/exp: 363 / 361.0Syn Z: 0.17

ClinVar Variant Classifications

127 submitted variants in ClinVar

Classification Summary

Pathogenic43
Likely Pathogenic2
VUS57
Likely Benign7
Benign1
43
Pathogenic
2
Likely Pathogenic
57
VUS
7
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
43
0
43
Likely Pathogenic
0
0
2
0
2
VUS
0
44
13
0
57
Likely Benign
0
4
0
3
7
Benign
0
0
1
0
1
Total048593110

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

P3H3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗