OTOA

Chr 16AR

otoancorin

Also known as: CT108, DFNB22

The encoded protein functions as an adhesion molecule that attaches the acellular gels to the apical surface of inner ear sensory epithelia. Mutations cause autosomal recessive deafness type 22 (DFNB22), typically presenting as congenital or early-onset hearing loss. The gene shows very low constraint against loss-of-function variants (pLI near zero), consistent with its autosomal recessive inheritance pattern where heterozygous carriers are unaffected.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.691 OMIM phenotype
Clinical SummaryOTOA
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Gene-Disease Validity (ClinGen)
nonsyndromic genetic hearing loss · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.69LOEUF
pLI 0.000
Z-score 3.29
OE 0.49 (0.350.69)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.28Z-score
OE missense 0.96 (0.891.04)
463 obs / 480.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.49 (0.350.69)
00.351.4
Missense OE0.96 (0.891.04)
00.61.4
Synonymous OE0.95
01.21.6
LoF obs/exp: 24 / 48.8Missense obs/exp: 463 / 480.4Syn Z: 0.51
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
limitedOTOA-related deafnessLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6258th %ile
GOF
0.6637th %ile
LOF
0.2775th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

OTOA · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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