OSGIN2

Chr 8

oxidative stress induced growth inhibitor family member 2

Also known as: C8orf1, hT41

The protein functions as a monooxygenase and is predicted to have growth factor activity involved in negative regulation of cell growth and possibly germ cell maturation. The gene is highly constrained against loss-of-function variants (LOEUF 0.427), suggesting mutations would likely cause severe developmental disorders. However, no specific disease associations have been established for OSGIN2 mutations in humans.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
34
P/LP submissions
0%
P/LP missense
0.43
LOEUF
Mechanism
Clinical SummaryOSGIN2
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.59) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
34 unique Pathogenic / Likely Pathogenic· 71 VUS of 125 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.43LOEUF
pLI 0.593
Z-score 3.66
OE 0.20 (0.100.43)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.88Z-score
OE missense 0.69 (0.610.78)
200 obs / 290.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.20 (0.100.43)
00.351.4
Missense OE0.69 (0.610.78)
00.61.4
Synonymous OE0.91
01.21.6
LoF obs/exp: 5 / 24.6Missense obs/exp: 200 / 290.1Syn Z: 0.73

ClinVar Variant Classifications

125 submitted variants in ClinVar

Classification Summary

Pathogenic34
VUS71
Likely Benign7
Benign2
34
Pathogenic
71
VUS
7
Likely Benign
2
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
34
0
34
Likely Pathogenic
0
0
0
0
0
VUS
0
64
7
0
71
Likely Benign
0
2
0
5
7
Benign
0
1
0
1
2
Total067416114

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

OSGIN2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗