OMA1

Chr 1

OMA1 zinc metallopeptidase

Also known as: 2010001O09Rik, MPRP-1, MPRP1, YKR087C, ZMPOMA1, peptidase

OMA1 encodes a mitochondrial metalloprotease that regulates mitochondrial quality control by cleaving target proteins including OPA1, DELE1, and UQCC3 in response to mitochondrial stress. Mutations cause autosomal recessive primary mitochondrial myopathy with early-onset progressive external ophthalmoplegia, ptosis, and exercise intolerance. The gene shows minimal constraint against loss-of-function variants (LOEUF 1.13), suggesting that complete loss of function may be tolerated in the heterozygous state.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.13
Clinical SummaryOMA1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.13LOEUF
pLI 0.000
Z-score 1.04
OE 0.78 (0.551.13)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.49Z-score
OE missense 0.92 (0.821.02)
248 obs / 270.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.78 (0.551.13)
00.351.4
Missense OE0.92 (0.821.02)
00.61.4
Synonymous OE0.91
01.21.6
LoF obs/exp: 20 / 25.7Missense obs/exp: 248 / 270.9Syn Z: 0.71
DN
0.7229th %ile
GOF
0.5758th %ile
LOF
0.3648th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

OMA1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗