OC90

Chr 8

otoconin 90

Also known as: PLA2L

The protein is a major component of otoconia (calcium carbonate structures in the inner ear) that acts as a scaffold for biomineralization by sequestering calcium and forming interconnecting fibrils between otoconia crystals. Mutations cause autosomal recessive benign recurrent vertigo, characterized by episodes of vertigo due to defective otoconia formation in the vestibular system. The gene shows minimal constraint against loss-of-function variants, consistent with its role in a non-life-threatening vestibular condition.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
0
P/LP submissions
P/LP missense
1.27
LOEUF
Mechanism
Clinical SummaryOC90
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.27LOEUF
pLI 0.000
Z-score 0.57
OE 0.87 (0.601.27)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-1.01Z-score
OE missense 1.18 (1.071.30)
301 obs / 255.5 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.87 (0.601.27)
00.351.4
Missense OE1.18 (1.071.30)
00.61.4
Synonymous OE1.28
01.21.6
LoF obs/exp: 19 / 21.9Missense obs/exp: 301 / 255.5Syn Z: -2.15

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

OC90 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC