NUP133

Chr 1AR

nucleoporin 133

Also known as: GAMOS8, NPHS18, hNUP133

NUP133 encodes a nucleoporin that forms part of nuclear pore complexes, which regulate transport of molecules between the nucleus and cytoplasm, and is involved in poly(A)+ RNA transport and kidney development. Mutations cause autosomal recessive Galloway-Mowat syndrome 8 and nephrotic syndrome type 18, affecting the kidneys and potentially other organ systems. The gene is highly constrained against loss-of-function variants (LOEUF 0.448), indicating that complete loss of protein function is likely pathogenic.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.452 OMIM phenotypes
Clinical SummaryNUP133
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Gene-Disease Validity (ClinGen)
nephrotic syndrome, type 18 · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.31) despite low pLI — interpret in context.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.45LOEUF
pLI 0.000
Z-score 5.17
OE 0.31 (0.220.45)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.02Z-score
OE missense 0.88 (0.820.95)
526 obs / 596.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.31 (0.220.45)
00.351.4
Missense OE0.88 (0.820.95)
00.61.4
Synonymous OE1.04
01.21.6
LoF obs/exp: 20 / 64.9Missense obs/exp: 526 / 596.4Syn Z: -0.49

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

NUP133 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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