NSUN3

Chr 3AR

NOP2/Sun RNA methyltransferase 3

Also known as: COXPD48, MST077, MSTP077

NSUN3 encodes a mitochondrial tRNA methyltransferase that methylates cytosine at the wobble position of mitochondrial tRNA(Met), enabling recognition of both AUG and AUA codons during mitochondrial protein synthesis. Mutations cause combined oxidative phosphorylation deficiency 48, a mitochondrial disorder affecting cellular energy production. The condition follows autosomal recessive inheritance.

Summary from RefSeq, OMIM, UniProt
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Primary Disease Associations & Inheritance

Combined oxidative phosphorylation deficiency 48MIM #619012
AR
0
Active trials
17
Pubs (1 yr)
0
P/LP submissions
P/LP missense
1.29
LOEUF
Mechanism
Clinical SummaryNSUN3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.29LOEUF
pLI 0.000
Z-score 0.67
OE 0.82 (0.541.29)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.31Z-score
OE missense 0.93 (0.821.06)
164 obs / 175.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.82 (0.541.29)
00.351.4
Missense OE0.93 (0.821.06)
00.61.4
Synonymous OE0.86
01.21.6
LoF obs/exp: 14 / 17.0Missense obs/exp: 164 / 175.4Syn Z: 0.92

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

NSUN3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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