NSMCE1

Chr 16

NSE1 component of SMC5/6 complex

Also known as: NSE1

NSMCE1 encodes a RING-type E3 ubiquitin ligase that functions within the SMC5-SMC6 complex to maintain genome integrity through DNA damage response and homologous recombination-mediated DNA repair. Mutations cause an autosomal recessive primary immunodeficiency characterized by growth retardation, developmental delay, facial dysmorphism, and increased susceptibility to infections. The gene shows tolerance to loss-of-function variants (pLI 0.00002, LOEUF 1.178), consistent with the recessive inheritance pattern.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.18
Clinical SummaryNSMCE1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.18LOEUF
pLI 0.000
Z-score 1.10
OE 0.68 (0.411.18)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.56Z-score
OE missense 0.88 (0.761.01)
141 obs / 160.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.68 (0.411.18)
00.351.4
Missense OE0.88 (0.761.01)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 9 / 13.3Missense obs/exp: 141 / 160.9Syn Z: 0.02

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

NSMCE1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC