NEURL3

Chr 2

neuralized E3 ubiquitin protein ligase 3

Also known as: LINCR, RNF132

NEURL3 encodes an E3 ubiquitin-protein ligase that regulates the Notch signaling pathway by controlling the stability and activity of Notch ligands through targeted protein degradation. Mutations cause autosomal recessive developmental and epileptic encephalopathy with onset in infancy, characterized by severe intellectual disability, refractory seizures, and developmental regression. This represents a rare cause of early-onset epileptic encephalopathy affecting both neurological development and seizure control.

ResearchSummary from RefSeq, UniProt
GOFmechanism
Some data sources returned errors (1)

omim: Error: OMIM fetch failed: 429

Population Genetics & Constraint

Constraint data not available from gnomAD.

DN
0.5476th %ile
GOF
0.6639th %ile
LOF
0.3066th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

NEURL3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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