NDC80

Chr 18

NDC80 kinetochore complex component

Also known as: HEC, HEC1, HsHec1, KNTC2, TID3, hsNDC80

The NDC80 protein is a component of the essential kinetochore-associated NDC80 complex that organizes microtubule-kinetochore interactions and is required for proper chromosome segregation during cell division. Mutations cause autosomal recessive primary microcephaly with intellectual disability and seizures, typically presenting in infancy. This gene is highly intolerant to loss-of-function variants, reflecting its essential role in cell division.

Summary from RefSeq, UniProt
Research Assistant →
1
Active trials
37
Pubs (1 yr)
131
P/LP submissions
0%
P/LP missense
0.70
LOEUF
DN
Mechanism· predicted
Clinical SummaryNDC80
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
126 unique Pathogenic / Likely Pathogenic· 78 VUS of 223 total submissions
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.70LOEUF
pLI 0.000
Z-score 3.03
OE 0.47 (0.330.70)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.84Z-score
OE missense 0.71 (0.640.79)
224 obs / 315.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.47 (0.330.70)
00.351.4
Missense OE0.71 (0.640.79)
00.61.4
Synonymous OE0.87
01.21.6
LoF obs/exp: 18 / 38.2Missense obs/exp: 224 / 315.9Syn Z: 1.08
DN
0.6744th %ile
GOF
0.4776th %ile
LOF
0.2678th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

223 submitted variants in ClinVar

Classification Summary

Pathogenic124
Likely Pathogenic2
VUS78
Likely Benign2
Benign3
124
Pathogenic
2
Likely Pathogenic
78
VUS
2
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
124
0
124
Likely Pathogenic
0
0
2
0
2
VUS
0
58
20
0
78
Likely Benign
0
1
1
0
2
Benign
0
0
1
2
3
Total0591482209

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

NDC80 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Literature
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