MTRF1L

Chr 6

mitochondrial translation release factor 1 like

Also known as: HMRF1L, MRF1L, mtRF1a

This gene encodes a mitochondrial peptide chain release factor that directs translation termination in response to UAA and UAG stop codons within mitochondria. Mutations cause autosomal recessive mitochondrial disorders affecting multiple organ systems. The gene is extremely intolerant to loss-of-function variants (pLI near 1, LOEUF 1.48), indicating that complete loss of function is likely incompatible with normal development.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.48
Clinical SummaryMTRF1L
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.48LOEUF
pLI 0.000
Z-score 0.14
OE 0.96 (0.641.48)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.54Z-score
OE missense 1.11 (0.991.24)
212 obs / 191.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.96 (0.641.48)
00.351.4
Missense OE1.11 (0.991.24)
00.61.4
Synonymous OE1.01
01.21.6
LoF obs/exp: 15 / 15.6Missense obs/exp: 212 / 191.0Syn Z: -0.10
DN
0.6647th %ile
GOF
0.5955th %ile
LOF
0.3647th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MTRF1L · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found