MTARC2

Chr 1

mitochondrial amidoxime reducing component 2

Also known as: MARC2, MOSC2

The MTARC2 protein is an outer mitochondrial membrane enzyme that reduces N-hydroxylated substrates using molybdenum as a cofactor, including toxic nucleotide base analogues and amidoxime prodrugs. This gene has very low constraint against loss-of-function variants (LOEUF 0.994), indicating that complete loss of protein function is generally tolerated. Currently, no established Mendelian disease phenotypes have been definitively linked to MTARC2 mutations in clinical practice.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 0.99
Clinical SummaryMTARC2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.99LOEUF
pLI 0.000
Z-score 1.59
OE 0.55 (0.320.99)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.43Z-score
OE missense 0.91 (0.791.04)
150 obs / 165.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.55 (0.320.99)
00.351.4
Missense OE0.91 (0.791.04)
00.61.4
Synonymous OE1.01
01.21.6
LoF obs/exp: 8 / 14.5Missense obs/exp: 150 / 165.6Syn Z: -0.07
DN
0.6358th %ile
GOF
0.4875th %ile
LOF
0.3647th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MTARC2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found