MRPL39

Chr 21AR

mitochondrial ribosomal protein L39

Also known as: C21orf92, COXPD59, L39mt, L5mt, MRP-L5, MRPL5, MSTP003, PRED22

This protein is a component of the large 39S subunit of mitochondrial ribosomes, which synthesize proteins essential for oxidative phosphorylation within mitochondria. Mutations cause combined oxidative phosphorylation deficiency 59, an autosomal recessive mitochondrial disorder. The gene shows low constraint to loss-of-function variation (pLI near 0), consistent with its recessive inheritance pattern.

Summary from RefSeq, OMIM
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Primary Disease Associations & Inheritance

Combined oxidative phosphorylation deficiency 59MIM #620646
AR
0
Active trials
1
Pubs (1 yr)
81
P/LP submissions
1%
P/LP missense
0.90
LOEUF
DN
Mechanism· predicted
Clinical SummaryMRPL39
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
71 unique Pathogenic / Likely Pathogenic· 56 VUS of 145 total submissions
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GeneReview available — MRPL39
Authoritative clinical overview · Recommended first read
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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.90LOEUF
pLI 0.000
Z-score 1.90
OE 0.56 (0.360.90)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.37Z-score
OE missense 1.08 (0.961.21)
206 obs / 191.5 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.56 (0.360.90)
00.351.4
Missense OE1.08 (0.961.21)
00.61.4
Synonymous OE1.12
01.21.6
LoF obs/exp: 12 / 21.5Missense obs/exp: 206 / 191.5Syn Z: -0.77
DN
0.6355th %ile
GOF
0.5367th %ile
LOF
0.3746th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

145 submitted variants in ClinVar

Classification Summary

Pathogenic65
Likely Pathogenic6
VUS56
Likely Benign1
Benign1
Conflicting1
65
Pathogenic
6
Likely Pathogenic
56
VUS
1
Likely Benign
1
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
65
0
65
Likely Pathogenic
0
1
5
0
6
VUS
0
49
7
0
56
Likely Benign
0
1
0
0
1
Benign
0
0
1
0
1
Conflicting
1
Total051780130

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MRPL39 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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