MPDU1

Chr 17AR

mannose-P-dolichol utilization defect 1

Also known as: CDGIF, HBEBP2BPA, Lec35, My008, PP3958, PQLC5, SL15, SLC66A5

The encoded endoplasmic reticulum membrane protein is required for normal utilization of mannose-dolichol phosphate in the synthesis of N-linked and O-linked oligosaccharides and GPI anchors. Mutations cause congenital disorder of glycosylation type If, which follows autosomal recessive inheritance. The gene shows low constraint to loss-of-function variation (pLI <0.001, LOEUF 1.31).

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.311 OMIM phenotype
Clinical SummaryMPDU1
🧬
Gene-Disease Validity (ClinGen)
MPDU1-congenital disorder of glycosylation · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.31LOEUF
pLI 0.000
Z-score 0.79
OE 0.75 (0.451.31)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.44Z-score
OE missense 0.89 (0.761.04)
112 obs / 125.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.75 (0.451.31)
00.351.4
Missense OE0.89 (0.761.04)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 9 / 11.9Missense obs/exp: 112 / 125.9Syn Z: 0.20
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveMPDU1-related congenital disorder of glycosylationLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.7131th %ile
GOF
0.7029th %ile
LOF
0.3067th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MPDU1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗