MPC1L

Chr X

mitochondrial pyruvate carrier 1 like

Also known as: SLC54A3

The protein mediates pyruvate uptake into mitochondria across the inner mitochondrial membrane. Mutations cause autosomal recessive developmental and epileptic encephalopathy with microcephaly. This condition typically presents in early infancy with seizures, developmental delay, and progressive microcephaly affecting the neurological system.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
0
P/LP submissions
P/LP missense
LOEUF
Multiple*
Mechanism· predicted

Population Genetics & Constraint

Constraint data not available from gnomAD.

DN
0.81top 10%
GOF
0.6832th %ile
LOF
0.3453th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MPC1L · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found