MORN5

Chr 9

MORN repeat containing 5

Also known as: C9orf113, C9orf18

Based on the provided information, MORN5 is predicted to be located in sperm flagella, but there is insufficient clinical data to determine what diseases result from mutations in this gene or the inheritance pattern. The predicted gain-of-function mechanism and very low pLI score (0.00008) suggest this gene is highly tolerant to loss-of-function mutations, but specific pathogenic mechanisms and associated neurological phenotypes are not established from the available data.

OMIMResearchSummary from RefSeq, Mechanism
MultiplemechanismLOEUF 1.47
Clinical SummaryMORN5
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
28 unique Pathogenic / Likely Pathogenic· 30 VUS of 62 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.47LOEUF
pLI 0.000
Z-score 0.58
OE 0.79 (0.451.47)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.41Z-score
OE missense 0.89 (0.751.05)
92 obs / 103.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.79 (0.451.47)
00.351.4
Missense OE0.89 (0.751.05)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 7 / 8.9Missense obs/exp: 92 / 103.7Syn Z: 0.30
DN
0.6744th %ile
GOF
0.6735th %ile
LOF
0.3260th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

62 submitted variants in ClinVar

Classification Summary

Pathogenic27
Likely Pathogenic1
VUS30
Benign1
27
Pathogenic
1
Likely Pathogenic
30
VUS
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
27
0
27
Likely Pathogenic
0
0
1
0
1
VUS
0
29
1
0
30
Likely Benign
0
0
0
0
0
Benign
0
0
1
0
1
Total02930059

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MORN5 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC