MOGS

Chr 2AR

mannosyl-oligosaccharide glucosidase

Also known as: CDG2B, CWH41, DER7, GCS1

This enzyme cleaves distal alpha-1,2-linked glucose residues from oligosaccharide precursors in the endoplasmic reticulum as the first step in N-linked glycosylation processing. Biallelic mutations cause congenital disorder of glycosylation type IIb (CDG-IIb), inherited in an autosomal recessive pattern. The gene shows very low intolerance to loss-of-function variants (pLI near zero), consistent with the recessive inheritance pattern where heterozygous carriers are typically unaffected.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
ARLOEUF 0.961 OMIM phenotype
Clinical SummaryMOGS
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Gene-Disease Validity (ClinGen)
MOGS-congenital disorder of glycosylation · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
42 unique Pathogenic / Likely Pathogenic· 329 VUS of 600 total submissions
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GeneReview available — MOGS
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.96LOEUF
pLI 0.000
Z-score 1.75
OE 0.66 (0.470.96)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.66Z-score
OE missense 0.91 (0.840.99)
434 obs / 474.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.66 (0.470.96)
00.351.4
Missense OE0.91 (0.840.99)
00.61.4
Synonymous OE1.05
01.21.6
LoF obs/exp: 21 / 31.6Missense obs/exp: 434 / 474.6Syn Z: -0.51

ClinVar Variant Classifications

600 submitted variants in ClinVar

Classification Summary

Pathogenic26
Likely Pathogenic16
VUS329
Likely Benign210
Benign6
Conflicting7
26
Pathogenic
16
Likely Pathogenic
329
VUS
210
Likely Benign
6
Benign
7
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
19
0
7
0
26
Likely Pathogenic
11
3
2
0
16
VUS
12
312
5
0
329
Likely Benign
0
3
29
178
210
Benign
0
0
4
2
6
Conflicting
7
Total4231847180594

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MOGS · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗