MKRN2

Chr 3

makorin ring finger protein 2

Also known as: HSPC070, RNF62

This gene encodes an E3 ubiquitin ligase that catalyzes ubiquitin attachment to target proteins for degradation and suppresses inflammatory responses by promoting degradation of the NF-kappaB component RELA/p65. The gene is highly constrained against loss-of-function variants (LOEUF 0.664), but no definitive human disease associations have been established in the provided data. Additional clinical and genetic studies would be needed to determine specific phenotypes and inheritance patterns associated with MKRN2 variants.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 0.66
Clinical SummaryMKRN2
Population Constraint (gnomAD)
Low constraint (pLI 0.01) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.66LOEUF
pLI 0.009
Z-score 2.67
OE 0.35 (0.200.66)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.52Z-score
OE missense 0.91 (0.811.01)
225 obs / 248.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.35 (0.200.66)
00.351.4
Missense OE0.91 (0.811.01)
00.61.4
Synonymous OE1.09
01.21.6
LoF obs/exp: 7 / 19.8Missense obs/exp: 225 / 248.0Syn Z: -0.67
DN
0.6648th %ile
GOF
0.6735th %ile
LOF
0.3260th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MKRN2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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