MIPEP

Chr 13AR

mitochondrial intermediate peptidase

Also known as: COXPD31, HMIP, MIP

The protein cleaves imported mitochondrial proteins to their mature size, representing the final processing step for nuclear-encoded proteins targeted to the mitochondrial matrix or inner membrane, particularly those involved in oxidative phosphorylation. Mutations cause combined oxidative phosphorylation deficiency 31 with autosomal recessive inheritance. The gene shows minimal constraint against loss-of-function variants (pLI near zero), which is consistent with recessive disease requiring biallelic mutations.

OMIMResearchSummary from RefSeq, OMIM, UniProt
ARLOEUF 1.031 OMIM phenotype
Clinical SummaryMIPEP
🧬
Gene-Disease Validity (ClinGen)
mitochondrial disease · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
13 unique Pathogenic / Likely Pathogenic· 113 VUS of 200 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.03LOEUF
pLI 0.000
Z-score 1.38
OE 0.76 (0.561.03)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.22Z-score
OE missense 0.97 (0.891.05)
366 obs / 378.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.76 (0.561.03)
00.351.4
Missense OE0.97 (0.891.05)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 28 / 37.1Missense obs/exp: 366 / 378.1Syn Z: 0.30

ClinVar Variant Classifications

200 submitted variants in ClinVar

Classification Summary

Pathogenic8
Likely Pathogenic5
VUS113
Likely Benign44
Benign3
Conflicting2
8
Pathogenic
5
Likely Pathogenic
113
VUS
44
Likely Benign
3
Benign
2
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
3
0
5
0
8
Likely Pathogenic
5
0
0
0
5
VUS
0
104
9
0
113
Likely Benign
0
2
17
25
44
Benign
0
1
2
0
3
Conflicting
2
Total81073325175

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MIPEP · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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