MIER1

Chr 1

MIER1 transcriptional regulator

Also known as: ER1, MI-ER1

The protein functions as a transcriptional repressor that regulates gene expression by recruiting histone deacetylase HDAC1 for chromatin silencing. Mutations cause neurodevelopmental disorder with intellectual disability, autism spectrum disorder, and behavioral abnormalities, inherited in an autosomal dominant pattern. The gene shows significant constraint against loss-of-function variants (LOEUF 0.42), indicating that such variants are likely pathogenic when they occur.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
1
Pubs (1 yr)
14
P/LP submissions
0%
P/LP missense
0.42
LOEUF
Mechanism
Clinical SummaryMIER1
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.23) despite low pLI — interpret in context.
📋
ClinVar Variants
14 unique Pathogenic / Likely Pathogenic· 61 VUS of 100 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.42LOEUF
pLI 0.289
Z-score 4.17
OE 0.23 (0.140.42)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.54Z-score
OE missense 0.75 (0.670.83)
218 obs / 292.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.23 (0.140.42)
00.351.4
Missense OE0.75 (0.670.83)
00.61.4
Synonymous OE0.87
01.21.6
LoF obs/exp: 8 / 34.4Missense obs/exp: 218 / 292.1Syn Z: 0.99

ClinVar Variant Classifications

100 submitted variants in ClinVar

Classification Summary

Pathogenic14
VUS61
Likely Benign2
14
Pathogenic
61
VUS
2
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
14
0
14
Likely Pathogenic
0
0
0
0
0
VUS
1
54
6
0
61
Likely Benign
0
1
0
1
2
Benign
0
0
0
0
0
Total15520177

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MIER1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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