MGP

Chr 12AR

matrix Gla protein

Also known as: GIG36, MGLAP, NTI

This protein is secreted by chondrocytes and vascular smooth muscle cells and functions as a vitamin K-dependent inhibitor of ectopic tissue calcification. Mutations cause Keutel syndrome, an autosomal recessive disorder characterized by abnormal cartilage calcification, peripheral pulmonary stenosis, and facial hypoplasia. The gene shows low constraint to loss-of-function variants (pLI 0.00004, LOEUF 1.66), consistent with its recessive inheritance pattern.

Summary from RefSeq, OMIM, UniProt
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Primary Disease Associations & Inheritance

Keutel syndromeMIM #245150
AR
2
Active trials
106
Pubs (1 yr)
48
P/LP submissions
0%
P/LP missense
1.66
LOEUF
LOF
Mechanism· G2P
Clinical SummaryMGP
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Gene-Disease Validity (ClinGen)
Keutel syndrome · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
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ClinVar Variants
44 unique Pathogenic / Likely Pathogenic· 51 VUS of 178 total submissions
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Clinical Trials
2 active or recruiting trials — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.66LOEUF
pLI 0.000
Z-score 0.21
OE 0.92 (0.521.66)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.12Z-score
OE missense 0.96 (0.791.18)
69 obs / 71.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.92 (0.521.66)
00.351.4
Missense OE0.96 (0.791.18)
00.61.4
Synonymous OE1.05
01.21.6
LoF obs/exp: 7 / 7.6Missense obs/exp: 69 / 71.8Syn Z: -0.20
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveMGP-related Keutel syndromeLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.78top 25%
GOF
0.5169th %ile
LOF
0.2385th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

178 submitted variants in ClinVar

Classification Summary

Pathogenic40
Likely Pathogenic4
VUS51
Likely Benign55
Benign17
Conflicting5
40
Pathogenic
4
Likely Pathogenic
51
VUS
55
Likely Benign
17
Benign
5
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
1
0
39
0
40
Likely Pathogenic
2
0
2
0
4
VUS
2
34
14
1
51
Likely Benign
0
3
41
11
55
Benign
0
2
15
0
17
Conflicting
5
Total53911112172

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MGP · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
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