MED12

Chr XXLDXLR

mediator complex subunit 12

Also known as: ARC240, CAGH45, FGS1, HDKR, HOPA, Kto, MED12S, OHDOX

The MED12 protein is essential for activating CDK8 kinase within the Mediator complex, which regulates transcription initiation and reinitiation rates by modulating interactions between Mediator and RNA polymerase II. Loss-of-function mutations cause multiple X-linked intellectual disability syndromes including Opitz-Kaveggia syndrome (FG syndrome), Lujan-Fryns syndrome, Ohdo syndrome, and Hardikar syndrome. The gene shows extreme intolerance to loss-of-function variants and follows X-linked inheritance patterns.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
LOFmechanismXLD/XLRLOEUF 0.074 OMIM phenotypes
Clinical SummaryMED12
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Gene-Disease Validity (ClinGen)
MED12-related intellectual disability syndrome · XLDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Dual constrained — LoF & missense intolerant
LoF Constraint
0.07LOEUF
pLI 1.000
Z-score 8.53
OE 0.02 (0.010.07)
Highly constrained

Among the most LoF-intolerant genes (~top 3%)

Missense Constraint
6.58Z-score
OE missense 0.38 (0.350.42)
343 obs / 897.8 exp
Constrained

Extremely missense-constrained (top ~0.01%)

Observed / Expected Ratios
LoF OE0.02 (0.010.07)
00.351.4
Missense OE0.38 (0.350.42)
00.61.4
Synonymous OE0.91
01.21.6
LoF obs/exp: 2 / 88.7Missense obs/exp: 343 / 897.8Syn Z: 1.25
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveMED12-related developmental disorderLOFmonoallelic_X_heterozygous
definitiveMED12-related Opitz-Kaveggia syndromeOTHERXLR
definitiveMED12-related Lujan-Fryns syndromeOTHERXLR
DN
0.17100th %ile
GOF
0.2796th %ile
LOF
0.89top 5%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.07

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MED12 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗